U.S. flag

An official website of the United States government

Format

Send to:

Choose Destination

Mucopolysaccharidosis, type vi, mild

MedGen UID:
865691
Concept ID:
C4017254
Finding
Synonym: MUCOPOLYSACCHARIDOSIS, TYPE VI, MILD
 
OMIM®: 611542

Recent clinical studies

Etiology

İnci A, Okur İ, Tümer L, Biberoğlu G, Öktem M, Ezgü F
Orphanet J Rare Dis 2021 Oct 19;16(1):438. doi: 10.1186/s13023-021-02060-4. PMID: 34666789Free PMC Article
Ademhan Tural D, Emiralioglu N, Dogru D, Ozsezen B, Ipek OF, Sunman B, Nayir Buyuksahin H, Guzelkas I, Ciki K, Kilic K, Vardar Yagli N, Yalcin E, Kiper N, Sivri S, Ozcelik U
Am J Med Genet A 2021 Aug;185(8):2306-2314. Epub 2021 May 7 doi: 10.1002/ajmg.a.62229. PMID: 33960649
Ahn J, Lee JJ, Park SI, Cho SY, Jin DK, Cho YS, Chung WH, Hong SH, Moon IJ
Otol Neurotol 2019 Dec;40(10):e955-e961. doi: 10.1097/MAO.0000000000002422. PMID: 31634273
Nicolas-Jilwan M, AlSayed M
Pediatr Radiol 2018 Sep;48(10):1503-1520. Epub 2018 May 11 doi: 10.1007/s00247-018-4139-3. PMID: 29752520
John A, Fagondes S, Schwartz I, Azevedo AC, Barrios P, Dalcin P, Menna-Barreto S, Giugliani R
Am J Med Genet A 2011 Jul;155A(7):1546-51. Epub 2011 Jun 2 doi: 10.1002/ajmg.a.33902. PMID: 21638759

Diagnosis

Kowalski T, Donoghue S, de Jong G, Mack HG
Ophthalmic Genet 2022 Oct;43(5):693-698. Epub 2022 Jun 6 doi: 10.1080/13816810.2022.2083184. PMID: 35658818
Lee CL, Chuang CK, Hsu CH, Chiu HC, Tu RY, Lo YT, Chang YH, Lin HY, Lin SP
J Formos Med Assoc 2022 Mar;121(3):712-717. Epub 2021 Aug 20 doi: 10.1016/j.jfma.2021.07.024. PMID: 34420841
Silveira MRMD, Buriti AKL, Martins AM, Gil D, Azevedo MF
Clinics (Sao Paulo) 2018 Dec 3;73:e523. doi: 10.6061/clinics/2018/e523. PMID: 30517303Free PMC Article
Valayannopoulos V, Nicely H, Harmatz P, Turbeville S
Orphanet J Rare Dis 2010 Apr 12;5:5. doi: 10.1186/1750-1172-5-5. PMID: 20385007Free PMC Article
Di Ferrante N, Hyman BH, Klish W, Donnelly PV, Nichols BL, Dutton RV
Johns Hopkins Med J 1974 Jul;135(1):42-54. PMID: 4276101

Therapy

Harmatz PR, Garcia P, Guffon N, Randolph LM, Shediac R, Braunlin E, Lachman RS, Decker C
J Inherit Metab Dis 2014 Mar;37(2):277-87. Epub 2013 Oct 10 doi: 10.1007/s10545-013-9654-7. PMID: 24108527Free PMC Article
Borlot F, Arantes PR, Quaio CR, Franco JF, Lourenço CM, Bertola DR, Kim CA
Brain Dev 2014 Aug;36(7):585-92. Epub 2013 Aug 21 doi: 10.1016/j.braindev.2013.07.016. PMID: 23972383
Leal GN, de Paula AC, Morhy SS, Andrade JL, Kim CA
Cardiol Young 2014 Apr;24(2):229-35. Epub 2013 Mar 5 doi: 10.1017/S1047951113000152. PMID: 23458163
Braunlin E, Rosenfeld H, Kampmann C, Johnson J, Beck M, Giugliani R, Guffon N, Ketteridge D, Sá Miranda CM, Scarpa M, Schwartz IV, Leão Teles E, Wraith JE, Barrios P, Dias da Silva E, Kurio G, Richardson M, Gildengorin G, Hopwood JJ, Imperiale M, Schatz A, Decker C, Harmatz P; MPS VI Study Group
J Inherit Metab Dis 2013 Mar;36(2):385-94. Epub 2012 Jun 5 doi: 10.1007/s10545-012-9481-2. PMID: 22669363Free PMC Article
Fahnehjelm KT, Chen E, Winiarski J
Acta Ophthalmol 2012 Aug;90(5):445-8. Epub 2011 Jan 14 doi: 10.1111/j.1755-3768.2010.02085.x. PMID: 21232085

Prognosis

Ademhan Tural D, Emiralioglu N, Dogru D, Ozsezen B, Ipek OF, Sunman B, Nayir Buyuksahin H, Guzelkas I, Ciki K, Kilic K, Vardar Yagli N, Yalcin E, Kiper N, Sivri S, Ozcelik U
Am J Med Genet A 2021 Aug;185(8):2306-2314. Epub 2021 May 7 doi: 10.1002/ajmg.a.62229. PMID: 33960649
Shapiro EG, Eisengart JB
Mol Genet Metab 2021 May;133(1):8-34. Epub 2021 Mar 11 doi: 10.1016/j.ymgme.2021.03.002. PMID: 33741271
Kılıç M, Dursun A, Coşkun T, Tokatlı A, Özgül RK, Yücel-Yılmaz D, Karaca M, Doğru D, Alehan D, Kadayıfçılar S, Genç A, Turan-Dizdar H, Gönüldaş B, Savcı S, Sağlam M, Aksoy C, Arslan U, Sivri HS
Am J Med Genet A 2017 Nov;173(11):2954-2967. Epub 2017 Sep 8 doi: 10.1002/ajmg.a.38459. PMID: 28884960
Borlot F, Arantes PR, Quaio CR, Franco JF, Lourenço CM, Bertola DR, Kim CA
Brain Dev 2014 Aug;36(7):585-92. Epub 2013 Aug 21 doi: 10.1016/j.braindev.2013.07.016. PMID: 23972383
Valayannopoulos V, Nicely H, Harmatz P, Turbeville S
Orphanet J Rare Dis 2010 Apr 12;5:5. doi: 10.1186/1750-1172-5-5. PMID: 20385007Free PMC Article

Clinical prediction guides

Ademhan Tural D, Emiralioglu N, Dogru D, Ozsezen B, Ipek OF, Sunman B, Nayir Buyuksahin H, Guzelkas I, Ciki K, Kilic K, Vardar Yagli N, Yalcin E, Kiper N, Sivri S, Ozcelik U
Am J Med Genet A 2021 Aug;185(8):2306-2314. Epub 2021 May 7 doi: 10.1002/ajmg.a.62229. PMID: 33960649
Garcia P, Phillips D, Johnson J, Martin K, Randolph LM, Rosenfeld H, Harmatz P
Mol Genet Metab 2021 May;133(1):100-108. Epub 2021 Mar 14 doi: 10.1016/j.ymgme.2021.03.006. PMID: 33775523
Shapiro EG, Eisengart JB
Mol Genet Metab 2021 May;133(1):8-34. Epub 2021 Mar 11 doi: 10.1016/j.ymgme.2021.03.002. PMID: 33741271
Borlot F, Arantes PR, Quaio CR, Franco JF, Lourenço CM, Bertola DR, Kim CA
Brain Dev 2014 Aug;36(7):585-92. Epub 2013 Aug 21 doi: 10.1016/j.braindev.2013.07.016. PMID: 23972383
Jurecka A, Zakharova E, Cimbalistiene L, Gusina N, Kulpanovich A, Golda A, Opoka-Winiarska V, Piotrowska E, Voskoboeva E, Tylki-Szymańska A
Am J Med Genet A 2013 Jun;161A(6):1291-9. Epub 2013 Apr 30 doi: 10.1002/ajmg.a.35905. PMID: 23633437

Supplemental Content

Recent activity

Your browsing activity is empty.

Activity recording is turned off.

Turn recording back on

See more...