U.S. flag

An official website of the United States government

Format

Send to:

Choose Destination

Myopathy, mitochondrial, late-onset

MedGen UID:
865060
Concept ID:
C4016623
Finding
Synonym: MYOPATHY, MITOCHONDRIAL, LATE-ONSET
 
OMIM®: 590070

Professional guidelines

PubMed

Surampalli A, Khare M, Kubrussi G, Wencel M, Tanaja J, Donkervoort S, Osann K, Simon M, Wallace D, Smith C, M McInerney-Leo A, Kimonis V
J Genet Couns 2015 Oct;24(5):842-50. Epub 2015 Feb 26 doi: 10.1007/s10897-015-9819-7. PMID: 25716352Free PMC Article
Faivre L, Cormier-Daire V, Chrétien D, Christoph von Kleist-Retzow J, Amiel J, Dommergues M, Saudubray JM, Dumez Y, Rötig A, Rustin P, Munnich A
Prenat Diagn 2000 Sep;20(9):732-7. doi: 10.1002/1097-0223(200009)20:9<732::aid-pd916>3.0.co;2-#. PMID: 11015702

Recent clinical studies

Etiology

Zhao B, Dai T, Zhao D, Ma X, Zhao C, Li L, Sun Y, Zhang Y, Yan Y, Lu JQ, Liu F, Yan C
Neurol Neuroimmunol Neuroinflamm 2022 Jul;9(4) Epub 2022 May 17 doi: 10.1212/NXI.0000000000001184. PMID: 35581006Free PMC Article
Deneubourg C, Ramm M, Smith LJ, Baron O, Singh K, Byrne SC, Duchen MR, Gautel M, Eskelinen EL, Fanto M, Jungbluth H
Autophagy 2022 Mar;18(3):496-517. Epub 2021 Aug 19 doi: 10.1080/15548627.2021.1943177. PMID: 34130600Free PMC Article
Heighton JN, Brady LI, Newman MC, Tarnopolsky MA
Mitochondrion 2019 Jan;44:15-19. Epub 2017 Dec 12 doi: 10.1016/j.mito.2017.12.006. PMID: 29246868
Viscomi C, Zeviani M
J Inherit Metab Dis 2017 Jul;40(4):587-599. Epub 2017 Mar 21 doi: 10.1007/s10545-017-0027-5. PMID: 28324239Free PMC Article
Stuerenburg HJ
Biochemistry (Mosc) 2000 Jul;65(7):862-5. PMID: 10951106

Diagnosis

Deneubourg C, Ramm M, Smith LJ, Baron O, Singh K, Byrne SC, Duchen MR, Gautel M, Eskelinen EL, Fanto M, Jungbluth H
Autophagy 2022 Mar;18(3):496-517. Epub 2021 Aug 19 doi: 10.1080/15548627.2021.1943177. PMID: 34130600Free PMC Article
Hussain Y, Miller S
Neurol Clin 2020 Aug;38(3):619-635. doi: 10.1016/j.ncl.2020.04.002. PMID: 32703473
Xu XB, Ji KQ, Lyu JW, Zhang S, Lyu XQ, Liu C, Li W, Yan CZ, Zhao YY
Chin Med J (Engl) 2019 Mar 20;132(6):716-718. doi: 10.1097/CM9.0000000000000139. PMID: 30741831Free PMC Article
Stuerenburg HJ
Biochemistry (Mosc) 2000 Jul;65(7):862-5. PMID: 10951106
Campanella G, Filla A, De Michele G
Acta Neurol (Napoli) 1992 Aug-Dec;14(4-6):408-19. PMID: 1293984

Therapy

Akar HT, Yıldız Y, Mutluay R, Tekin E, Tokatlı A
CEN Case Rep 2024 Apr;13(2):81-85. Epub 2023 Jun 21 doi: 10.1007/s13730-023-00804-8. PMID: 37341884Free PMC Article
Zhao B, Dai T, Zhao D, Ma X, Zhao C, Li L, Sun Y, Zhang Y, Yan Y, Lu JQ, Liu F, Yan C
Neurol Neuroimmunol Neuroinflamm 2022 Jul;9(4) Epub 2022 May 17 doi: 10.1212/NXI.0000000000001184. PMID: 35581006Free PMC Article
De Paepe B
Biomolecules 2019 Jan 7;9(1) doi: 10.3390/biom9010015. PMID: 30621041Free PMC Article
Heighton JN, Brady LI, Newman MC, Tarnopolsky MA
Mitochondrion 2019 Jan;44:15-19. Epub 2017 Dec 12 doi: 10.1016/j.mito.2017.12.006. PMID: 29246868
Gironi M, Lamperti C, Nemni R, Moggio M, Comi G, Guerini FR, Ferrante P, Canal N, Naini A, Bresolin N, DiMauro S
Neurology 2004 Mar 9;62(5):818-20. doi: 10.1212/01.wnl.0000113719.67643.b7. PMID: 15007142

Prognosis

Domínguez-González C, Fernández-Torrón R, Moore U, de Fuenmayor-Fernández de la Hoz CP, Vélez-Gómez B, Cabezas JA, Alonso-Pérez J, González-Mera L, Olivé M, García-García J, Moris G, León Hernández JC, Muelas N, Servian-Morilla E, Martin MA, Díaz-Manera J, Paradas C
J Neurol 2022 Jul;269(7):3550-3562. Epub 2022 Mar 14 doi: 10.1007/s00415-021-10957-0. PMID: 35286480Free PMC Article
Deneubourg C, Ramm M, Smith LJ, Baron O, Singh K, Byrne SC, Duchen MR, Gautel M, Eskelinen EL, Fanto M, Jungbluth H
Autophagy 2022 Mar;18(3):496-517. Epub 2021 Aug 19 doi: 10.1080/15548627.2021.1943177. PMID: 34130600Free PMC Article
Domínguez-González C, Hernández-Laín A, Rivas E, Hernández-Voth A, Sayas Catalán J, Fernández-Torrón R, Fuiza-Luces C, García García J, Morís G, Olivé M, Miralles F, Díaz-Manera J, Caballero C, Méndez-Ferrer B, Martí R, García Arumi E, Badosa MC, Esteban J, Jimenez-Mallebrera C, Encinar AB, Arenas J, Hirano M, Martin MÁ, Paradas C
Orphanet J Rare Dis 2019 May 6;14(1):100. doi: 10.1186/s13023-019-1071-z. PMID: 31060578Free PMC Article
Garone C, Taylor RW, Nascimento A, Poulton J, Fratter C, Domínguez-González C, Evans JC, Loos M, Isohanni P, Suomalainen A, Ram D, Hughes MI, McFarland R, Barca E, Lopez Gomez C, Jayawant S, Thomas ND, Manzur AY, Kleinsteuber K, Martin MA, Kerr T, Gorman GS, Sommerville EW, Chinnery PF, Hofer M, Karch C, Ralph J, Cámara Y, Madruga-Garrido M, Domínguez-Carral J, Ortez C, Emperador S, Montoya J, Chakrapani A, Kriger JF, Schoenaker R, Levin B, Thompson JLP, Long Y, Rahman S, Donati MA, DiMauro S, Hirano M
J Med Genet 2018 Aug;55(8):515-521. Epub 2018 Mar 30 doi: 10.1136/jmedgenet-2017-105012. PMID: 29602790Free PMC Article
El-Hattab AW, Wang J, Dai H, Almannai M, Staufner C, Alfadhel M, Gambello MJ, Prasun P, Raza S, Lyons HJ, Afqi M, Saleh MAM, Faqeih EA, Alzaidan HI, Alshenqiti A, Flore LA, Hertecant J, Sacharow S, Barbouth DS, Murayama K, Shah AA, Lin HC, Wong LC
Hum Mutat 2018 Apr;39(4):461-470. Epub 2018 Jan 13 doi: 10.1002/humu.23387. PMID: 29282788

Clinical prediction guides

Garone C, Taylor RW, Nascimento A, Poulton J, Fratter C, Domínguez-González C, Evans JC, Loos M, Isohanni P, Suomalainen A, Ram D, Hughes MI, McFarland R, Barca E, Lopez Gomez C, Jayawant S, Thomas ND, Manzur AY, Kleinsteuber K, Martin MA, Kerr T, Gorman GS, Sommerville EW, Chinnery PF, Hofer M, Karch C, Ralph J, Cámara Y, Madruga-Garrido M, Domínguez-Carral J, Ortez C, Emperador S, Montoya J, Chakrapani A, Kriger JF, Schoenaker R, Levin B, Thompson JLP, Long Y, Rahman S, Donati MA, DiMauro S, Hirano M
J Med Genet 2018 Aug;55(8):515-521. Epub 2018 Mar 30 doi: 10.1136/jmedgenet-2017-105012. PMID: 29602790Free PMC Article
Lee HN, Eom S, Kim SH, Kang HC, Lee JS, Kim HD, Lee YM
Pediatr Neurol 2016 Nov;64:59-65. Epub 2016 Aug 26 doi: 10.1016/j.pediatrneurol.2016.08.016. PMID: 27671241
Winter L, Wiche G
Acta Neuropathol 2013 Jan;125(1):77-93. Epub 2012 Aug 3 doi: 10.1007/s00401-012-1026-0. PMID: 22864774
Johnston W, Karpati G, Carpenter S, Arnold D, Shoubridge EA
Ann Neurol 1995 Jan;37(1):16-23. doi: 10.1002/ana.410370106. PMID: 7818252
Wallace DC, Lott MT, Shoffner JM, Brown MD
J Inherit Metab Dis 1992;15(4):472-9. doi: 10.1007/BF01799605. PMID: 1528007

Recent systematic reviews

Finsterer J
J Clin Neuromuscul Dis 2023 Mar 1;24(3):140-146. doi: 10.1097/CND.0000000000000422. PMID: 36809201

Supplemental Content

Table of contents

    Clinical resources

    Practice guidelines

    • PubMed
      See practice and clinical guidelines in PubMed. The search results may include broader topics and may not capture all published guidelines. See the FAQ for details.

    Consumer resources

    Recent activity

    Your browsing activity is empty.

    Activity recording is turned off.

    Turn recording back on

    See more...