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nstd238 (OuYang et al. 2024)

Organism:
Human
Study Type:
Case-Set
Submitter:
Yujin Qu
Description:
The association between biomarkers, phenotypes, and motor milestones were assessed in Chinese SMA patients. Four biomarkers, survival motor neuron 2 (SMN2) copies, neuronal apoptosis inhibitory protein (NAIP) copies, full-length SMN2 (fl-SMN2), and F-actin bundling protein plastin 3 (PLS3) transcript levels were included and their relationships with disease severity and progression were investigated. All four biomarkers were found to correlate with the disease severity and the fl-SMN2 transcript level elevated with an increase in SMN2 copies. An association was observed between motor milestone degeneration/and the SMN2 copies, NAIP copies, and fl-SMN2 level. See Variant Summary counts for nstd238 in dbVar Variant Summary.

Detailed Information: Download 3 Variant Regions, Download 317 Variant Calls, Download Both, FTP

Variant Summary

Assembly used for analysis:
Submitted: GRCh38 (hg38)

Sequence IDChrNumber of Variant RegionsNumber of Variant CallsPlacement typeLink to graphical display
NC_000005.10Chr53317SubmittedNC_000005.10

Samplesets

Number of Samplesets: 3

Sampleset ID:
1
Name:
SMA1
Sampleset Type:
Case
Description:
spinal muscular atrophy type 1
Size:
30
Organisms:
Homo sapiens
Sampleset Phenotype(s):
SPINAL MUSCULAR ATROPHY, TYPE I; SMA1
  • Download Samples as CSV file
  • Samples for sampleset 1
    Sample IDSubject ID Subject Phenotype
    CIP2220CIP2220spinal muscular atrophy, type i; sma1
    CIP1978CIP1978spinal muscular atrophy, type i; sma1
    CIP2207CIP2207spinal muscular atrophy, type i; sma1
    CIP1927CIP1927spinal muscular atrophy, type i; sma1
    CIP0266CIP0266spinal muscular atrophy, type i; sma1
    CIP1901CIP1901spinal muscular atrophy, type i; sma1
    CIP2140CIP2140spinal muscular atrophy, type i; sma1
    CIP1976CIP1976spinal muscular atrophy, type i; sma1
    CIP2128CIP2128spinal muscular atrophy, type i; sma1
    CIP1935CIP1935spinal muscular atrophy, type i; sma1
    CIP2202CIP2202spinal muscular atrophy, type i; sma1
    CIP2015CIP2015spinal muscular atrophy, type i; sma1
    CIP2125CIP2125spinal muscular atrophy, type i; sma1
    CIP1984CIP1984spinal muscular atrophy, type i; sma1
    CIP1909CIP1909spinal muscular atrophy, type i; sma1
    CIP1940CIP1940spinal muscular atrophy, type i; sma1
    CIP2109CIP2109spinal muscular atrophy, type i; sma1
    CIP1941CIP1941spinal muscular atrophy, type i; sma1
    CIP1979CIP1979spinal muscular atrophy, type i; sma1
    CIP2107CIP2107spinal muscular atrophy, type i; sma1
    CIP2026CIP2026spinal muscular atrophy, type i; sma1
    CIP2135CIP2135spinal muscular atrophy, type i; sma1
    CIP2219CIP2219spinal muscular atrophy, type i; sma1
    CIP1936CIP1936spinal muscular atrophy, type i; sma1
    CIP2137CIP2137spinal muscular atrophy, type i; sma1
    CIP1903CIP1903spinal muscular atrophy, type i; sma1
    CIP0424CIP0424spinal muscular atrophy, type i; sma1
    CIP0530CIP0530spinal muscular atrophy, type i; sma1
    CIP1963CIP1963spinal muscular atrophy, type i; sma1
    CIP1914CIP1914spinal muscular atrophy, type i; sma1
    Sampleset ID:
    2
    Name:
    SMA2
    Sampleset Type:
    Case
    Description:
    spinal muscular atrophy type 2
    Size:
    56
    Organisms:
    Homo sapiens
    Sampleset Phenotype(s):
    SPINAL MUSCULAR ATROPHY, TYPE II; SMA2
  • Download Samples as CSV file
  • Samples for sampleset 2
    Sample IDSubject ID Subject Phenotype
    CIP2108CIP2108spinal muscular atrophy, type ii; sma2
    CIP2225CIP2225spinal muscular atrophy, type ii; sma2
    CIP2001CIP2001spinal muscular atrophy, type ii; sma2
    CIP2110CIP2110spinal muscular atrophy, type ii; sma2
    CIP2014CIP2014spinal muscular atrophy, type ii; sma2
    CIP2007CIP2007spinal muscular atrophy, type ii; sma2
    CIP1912CIP1912spinal muscular atrophy, type ii; sma2
    CIP1777CIP1777spinal muscular atrophy, type ii; sma2
    CIP1958CIP1958spinal muscular atrophy, type ii; sma2
    CIP2224CIP2224spinal muscular atrophy, type ii; sma2
    CIP1977CIP1977spinal muscular atrophy, type ii; sma2
    CIP2139CIP2139spinal muscular atrophy, type ii; sma2
    CIP2229CIP2229spinal muscular atrophy, type ii; sma2
    CIP2011CIP2011spinal muscular atrophy, type ii; sma2
    CIP1919CIP1919spinal muscular atrophy, type ii; sma2
    CIP0193CIP0193spinal muscular atrophy, type ii; sma2
    CIP1970CIP1970spinal muscular atrophy, type ii; sma2
    CIP1911CIP1911spinal muscular atrophy, type ii; sma2
    CIP1955CIP1955spinal muscular atrophy, type ii; sma2
    CIP1922CIP1922spinal muscular atrophy, type ii; sma2
    CIP2119CIP2119spinal muscular atrophy, type ii; sma2
    CIP0143CIP0143spinal muscular atrophy, type ii; sma2
    CIP2017CIP2017spinal muscular atrophy, type ii; sma2
    CIP2211CIP2211spinal muscular atrophy, type ii; sma2
    CIP1980CIP1980spinal muscular atrophy, type ii; sma2
    CIP2117CIP2117spinal muscular atrophy, type ii; sma2
    CIP2020CIP2020spinal muscular atrophy, type ii; sma2
    CIP1973CIP1973spinal muscular atrophy, type ii; sma2
    CIP1905CIP1905spinal muscular atrophy, type ii; sma2
    CIP2101CIP2101spinal muscular atrophy, type ii; sma2
    CIP0169CIP0169spinal muscular atrophy, type ii; sma2
    CIP1924CIP1924spinal muscular atrophy, type ii; sma2
    CIP1950CIP1950spinal muscular atrophy, type ii; sma2
    CIP1961CIP1961spinal muscular atrophy, type ii; sma2
    CIP2131CIP2131spinal muscular atrophy, type ii; sma2
    CIP2218CIP2218spinal muscular atrophy, type ii; sma2
    CIP0062CIP0062spinal muscular atrophy, type ii; sma2
    CIP1921CIP1921spinal muscular atrophy, type ii; sma2
    CIP2205CIP2205spinal muscular atrophy, type ii; sma2
    CIP1904CIP1904spinal muscular atrophy, type ii; sma2
    CIP2138CIP2138spinal muscular atrophy, type ii; sma2
    CIP1913CIP1913spinal muscular atrophy, type ii; sma2
    CIP1928CIP1928spinal muscular atrophy, type ii; sma2
    CIP1946CIP1946spinal muscular atrophy, type ii; sma2
    CIP1906CIP1906spinal muscular atrophy, type ii; sma2
    CIP1962CIP1962spinal muscular atrophy, type ii; sma2
    CIP2217CIP2217spinal muscular atrophy, type ii; sma2
    CIP0097CIP0097spinal muscular atrophy, type ii; sma2
    CIP1948CIP1948spinal muscular atrophy, type ii; sma2
    CIP2146CIP2146spinal muscular atrophy, type ii; sma2
    CIP0574CIP0574spinal muscular atrophy, type ii; sma2
    CIP2129CIP2129spinal muscular atrophy, type ii; sma2
    CIP1920CIP1920spinal muscular atrophy, type ii; sma2
    CIP1931CIP1931spinal muscular atrophy, type ii; sma2
    CIP1949CIP1949spinal muscular atrophy, type ii; sma2
    CIP1929CIP1929spinal muscular atrophy, type ii; sma2
    Sampleset ID:
    3
    Name:
    SMA3
    Sampleset Type:
    Case
    Description:
    spinal muscular atrophy type 3
    Size:
    37
    Organisms:
    Homo sapiens
    Sampleset Phenotype(s):
    SPINAL MUSCULAR ATROPHY, TYPE III; SMA3
  • Download Samples as CSV file
  • Samples for sampleset 3
    Sample IDSubject ID Subject Phenotype
    CIP2123CIP2123spinal muscular atrophy, type iii; sma3
    CIP1966-4CIP1966-4spinal muscular atrophy, type iii; sma3
    CIP1967CIP1967spinal muscular atrophy, type iii; sma3
    CIP0524CIP0524spinal muscular atrophy, type iii; sma3
    CIP2018-1CIP2018spinal muscular atrophy, type iii; sma3
    CIP1974CIP1974spinal muscular atrophy, type iii; sma3
    CIP0587CIP0587spinal muscular atrophy, type iii; sma3
    CIP1959CIP1959spinal muscular atrophy, type iii; sma3
    CIP1953CIP1953spinal muscular atrophy, type iii; sma3
    CIP1943CIP1943spinal muscular atrophy, type iii; sma3
    CIP1938CIP1938spinal muscular atrophy, type iii; sma3
    CIP2005CIP2005spinal muscular atrophy, type iii; sma3
    CIP1982CIP1982spinal muscular atrophy, type iii; sma3
    CIP1910CIP1910spinal muscular atrophy, type iii; sma3
    CIP2147CIP2147spinal muscular atrophy, type iii; sma3
    CIP1902CIP1902spinal muscular atrophy, type iii; sma3
    CIP0202CIP0202spinal muscular atrophy, type iii; sma3
    CIP1930CIP1930spinal muscular atrophy, type iii; sma3
    CIP2221-4CIP2221-4spinal muscular atrophy, type iii; sma3
    CIP2114CIP2114spinal muscular atrophy, type iii; sma3
    CIP2031CIP2031spinal muscular atrophy, type iii; sma3
    CIP2029CIP2029spinal muscular atrophy, type iii; sma3
    CIP2127CIP2127spinal muscular atrophy, type iii; sma3
    CIP2018-4CIP2018-4spinal muscular atrophy, type iii; sma3
    CIP1918CIP1918spinal muscular atrophy, type iii; sma3
    CIP2008CIP2008spinal muscular atrophy, type iii; sma3
    CIP1923CIP1923spinal muscular atrophy, type iii; sma3
    CIP1916CIP1916spinal muscular atrophy, type iii; sma3
    CIP1966-1CIP1966-1spinal muscular atrophy, type iii; sma3
    CIP2122CIP2122spinal muscular atrophy, type iii; sma3
    CIP1945CIP1945spinal muscular atrophy, type iii; sma3
    CIP1834CIP1834spinal muscular atrophy, type iii; sma3
    CIP2115CIP2115spinal muscular atrophy, type iii; sma3
    CIP2143CIP2143spinal muscular atrophy, type iii; sma3
    CIP1907CIP1907spinal muscular atrophy, type iii; sma3
    CIP1964CIP1964spinal muscular atrophy, type iii; sma3
    CIP1954CIP1954spinal muscular atrophy, type iii; sma3

    Experimental Details

    Experiment IDTypeMethodAnalysisNumber of Variant Calls
    1GenotypingMLPAGenotyping317

    Validations

    No validation data were submitted for this study.

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