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Paroxysmal choreoathetosis

MedGen UID:
343687
Concept ID:
C1851936
Disease or Syndrome
Synonyms: Choreoathetosis, episodic; Choreoathetosis, intermittent; Choreoathetosis, paroxysmal
SNOMED CT: Paroxysmal dyskinesia (49949003); Paroxysmal choreoathetosis (49949003)
 
HPO: HP:0007098

Definition

Episodes of choreoathetosis that can occur following triggers such as quick voluntary movements. [from HPO]

Term Hierarchy

CClinical test,  RResearch test,  OOMIM,  GGeneReviews,  VClinVar  
  • Paroxysmal choreoathetosis

Conditions with this feature

Striatonigral degeneration, infantile, mitochondrial
MedGen UID:
374113
Concept ID:
C1839022
Disease or Syndrome
Infantile convulsions and choreoathetosis
MedGen UID:
356123
Concept ID:
C1865926
Disease or Syndrome
PRRT2-related disorder, caused by heterozygous pathogenic variants in the gene PRRT2 (associated with aberrant synaptic transmission), is characterized by three core episodic neurologic phenotypes: epilepsy, movement disorder, and migraine. Age at onset and phenotypes range from neonatal/infantile (self-limited [familial] infantile epilepsy), to childhood (childhood absence epilepsy), to adolescence to adulthood (paroxysmal kinesigenic dyskinesia [PKD] or migraine). As individuals with PRRT2-related disorder age, they may exhibit one of more of these core phenotypes in various combinations, either concurrently or sequentially. Additionally, family members with the same pathogenic PRRT2 variant may display different core phenotypes.
Paroxysmal nonkinesigenic dyskinesia 1
MedGen UID:
1631383
Concept ID:
C4551506
Disease or Syndrome
Familial paroxysmal nonkinesigenic dyskinesia (PNKD) is characterized by unilateral or bilateral involuntary movements. Attacks are typically precipitated by coffee, tea, or alcohol; they can also be triggered by excitement, stress, or fatigue, or can be spontaneous. Attacks involve dystonic posturing with choreic and ballistic movements, may be accompanied by a preceding aura, occur while the individual is awake, and are not associated with seizures. Attacks last minutes to hours and rarely occur more than once per day. Attack frequency, duration, severity, and combinations of symptoms vary within and among families. Age of onset is typically in childhood or early teens but can be as late as age 50 years.
Episodic kinesigenic dyskinesia 1
MedGen UID:
1636366
Concept ID:
C4552000
Disease or Syndrome
PRRT2-related disorder, caused by heterozygous pathogenic variants in the gene PRRT2 (associated with aberrant synaptic transmission), is characterized by three core episodic neurologic phenotypes: epilepsy, movement disorder, and migraine. Age at onset and phenotypes range from neonatal/infantile (self-limited [familial] infantile epilepsy), to childhood (childhood absence epilepsy), to adolescence to adulthood (paroxysmal kinesigenic dyskinesia [PKD] or migraine). As individuals with PRRT2-related disorder age, they may exhibit one of more of these core phenotypes in various combinations, either concurrently or sequentially. Additionally, family members with the same pathogenic PRRT2 variant may display different core phenotypes.

Professional guidelines

PubMed

Deuschl G
Neurodegener Dis Manag 2016 Dec;6(6s):31-35. doi: 10.2217/nmt-2016-0053. PMID: 27874491
Wang BJ, Chang YC
Ther Drug Monit 1985;7(1):81-2. doi: 10.1097/00007691-198503000-00013. PMID: 3887671

Recent clinical studies

Etiology

Pery R, Gudmundsdottir H, Nagorney DM, Pencovich N, Smoot RL, Thiels CA, Truty MJ, Vierkant RA, Warner SG, Kendrick ML, Cleary SP
HPB (Oxford) 2023 Mar;25(3):339-346. Epub 2022 Dec 31 doi: 10.1016/j.hpb.2022.12.006. PMID: 36707278
Javle M, Lee S, Azad NS, Borad MJ, Kate Kelley R, Sivaraman S, Teschemaker A, Chopra I, Janjan N, Parasuraman S, Bekaii-Saab TS
Oncologist 2022 Oct 1;27(10):874-883. doi: 10.1093/oncolo/oyac150. PMID: 35972334Free PMC Article
Waln O, Jankovic J
Neurol Clin 2015 Feb;33(1):137-52. doi: 10.1016/j.ncl.2014.09.014. PMID: 25432727
Liu XR, Wu M, He N, Meng H, Wen L, Wang JL, Zhang MP, Li WB, Mao X, Qin JM, Li BM, Tang B, Deng YH, Shi YW, Su T, Yi YH, Tang BS, Liao WP
Genes Brain Behav 2013 Mar;12(2):234-40. Epub 2012 Dec 21 doi: 10.1111/gbb.12008. PMID: 23190448
Lance JW
Ann Neurol 1977 Oct;2(4):285-93. doi: 10.1002/ana.410020405. PMID: 617268

Diagnosis

Waln O, Jankovic J
Neurol Clin 2015 Feb;33(1):137-52. doi: 10.1016/j.ncl.2014.09.014. PMID: 25432727
Klein C, Vieregge P, Kömpf D
Mov Disord 1997 Mar;12(2):254-5. doi: 10.1002/mds.870120223. PMID: 9087991
Lüders HO
Eur Neurol 1996;36 Suppl 1:20-3. doi: 10.1159/000118879. PMID: 8791017
Tassinari CA, Fine RD
Proc Aust Assoc Neurol 1969;6:71-5. PMID: 5358018
Perez-Borja C, Tassinari AC, Swanson AG
Epilepsia 1967 Dec;8(4):260-70. doi: 10.1111/j.1528-1157.1967.tb04442.x. PMID: 5238718

Therapy

Yu X, Che F, Zhang X, Yang L, Zhu L, Xu N, Qiu S, Li Y
Epilepsia Open 2024 Oct;9(5):1658-1669. Epub 2024 Aug 14 doi: 10.1002/epi4.13028. PMID: 39141400Free PMC Article
Gordon N
Brain Dev 1998 Jan;20(1):9-13. doi: 10.1016/s0387-7604(97)00086-7. PMID: 9533553
Rani Jusoh
Med J Malaysia 1983 Sep;38(3):224-7. PMID: 6672565
Tassinari CA, Fine RD
Proc Aust Assoc Neurol 1969;6:71-5. PMID: 5358018
Kertesz A
Neurology 1967 Jul;17(7):680-90. doi: 10.1212/wnl.17.7.680. PMID: 6067487

Prognosis

Javle M, Lee S, Azad NS, Borad MJ, Kate Kelley R, Sivaraman S, Teschemaker A, Chopra I, Janjan N, Parasuraman S, Bekaii-Saab TS
Oncologist 2022 Oct 1;27(10):874-883. doi: 10.1093/oncolo/oyac150. PMID: 35972334Free PMC Article
Yang X, Zhang Y, Xu X, Wang S, Yang Z, Wu Y, Liu X, Wu X
BMC Neurol 2013 Dec 26;13:209. doi: 10.1186/1471-2377-13-209. PMID: 24370076Free PMC Article
Heron SE, Dibbens LM
J Med Genet 2013 Mar;50(3):133-9. Epub 2013 Jan 23 doi: 10.1136/jmedgenet-2012-101406. PMID: 23343561
Kato N, Sadamatsu M, Kikuchi T, Niikawa N, Fukuyama Y
Epilepsy Res 2006 Aug;70 Suppl 1:S174-84. Epub 2006 Aug 9 doi: 10.1016/j.eplepsyres.2006.02.009. PMID: 16901678
Nardocci N, Lamperti E, Rumi V, Angelini L
Dev Med Child Neurol 1989 Oct;31(5):670-4. doi: 10.1111/j.1469-8749.1989.tb04054.x. PMID: 2806747

Clinical prediction guides

Yang X, Zhang Y, Xu X, Wang S, Yang Z, Wu Y, Liu X, Wu X
BMC Neurol 2013 Dec 26;13:209. doi: 10.1186/1471-2377-13-209. PMID: 24370076Free PMC Article
Heron SE, Dibbens LM
J Med Genet 2013 Mar;50(3):133-9. Epub 2013 Jan 23 doi: 10.1136/jmedgenet-2012-101406. PMID: 23343561
Liu XR, Wu M, He N, Meng H, Wen L, Wang JL, Zhang MP, Li WB, Mao X, Qin JM, Li BM, Tang B, Deng YH, Shi YW, Su T, Yi YH, Tang BS, Liao WP
Genes Brain Behav 2013 Mar;12(2):234-40. Epub 2012 Dec 21 doi: 10.1111/gbb.12008. PMID: 23190448
Valente EM, Spacey SD, Wali GM, Bhatia KP, Dixon PH, Wood NW, Davis MB
Brain 2000 Oct;123 ( Pt 10):2040-5. doi: 10.1093/brain/123.10.2040. PMID: 11004121
Tomita Ha, Nagamitsu S, Wakui K, Fukushima Y, Yamada K, Sadamatsu M, Masui A, Konishi T, Matsuishi T, Aihara M, Shimizu K, Hashimoto K, Mineta M, Matsushima M, Tsujita T, Saito M, Tanaka H, Tsuji S, Takagi T, Nakamura Y, Nanko S, Kato N, Nakane Y, Niikawa N
Am J Hum Genet 1999 Dec;65(6):1688-97. doi: 10.1086/302682. PMID: 10577923Free PMC Article

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